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Journals / Acta Orthopaedica et Traumatologica Turcica / 2026 / Cilt: 49 Sayı: 2

Osteofibrous dysplasia-like adamantinoma in a 3-month-old male infant: a case report

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Halil Buldu
Tuncay Centel
Hale Kirimlioglu
Yalin Dirik
Pages
210–212
Publication Date
2015-05-22
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AI Summary & Key Takeaways

AI Insight
⚡ TL;DR(Too Long; Didn't Read)

OFDLA is typically regarded as a benign lesion; however, due to its convertibility into classical adamantinoma, it is recommended to evaluate it as a pre-malignant lesion.

📌 3 Key Takeaways

🎯
Objective & Hypothesis:We report a case of a very rarely seen osteofibrous dysplasia-like adamantinoma (OFDLA) of the lower leg in a 3-month-old male infant, making it the youngest case in the literature.
📊
Key Findings & Data:OFDLA is typically regarded as a benign lesion; however, due to its convertibility into classical adamantinoma, it is recommended to evaluate it as a pre-malignant lesion.
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Conclusion & Impact:Patient experienced good outcomes and did not experience any local relapse in the 3-year follow-up.
🔬Design:Araştırma Makalesi
📍Scope:Comprehensive Sample
⚙️Variables:Adamantinoma · osteofibröz displazi · osteofibröz displazi benzeri adamantinoma

Abstract

We report a case of a very rarely seen osteofibrous dysplasia-like adamantinoma (OFDLA) of the lower leg in a 3-month-old male infant, making it the youngest case in the literature. OFDLA is typically regarded as a benign lesion; however, due to its convertibility into classical adamantinoma, it is recommended to evaluate it as a pre-malignant lesion. After OFDLA diagnosis with biopsy, our case underwent surgical resection and reconstruction with a large allograft. Patient experienced good outcomes and did not experience any local relapse in the 3-year follow-up.

Özet

Kemik tümörleri içerisinde nadir görülen osteofibrözdisplazi benzeri adamantinoma (OFDBA)’nın saptandığı ve literatürde bildirilen en küçük yaştaki olgu tanımlanmıştır. OFDBA, osteofibröz displa- zi ve klasik adamantinomaya radyolojik, histopatolojik olarak benzerlik göstermektedir. OFDBA’nın klasik adamantinomaya dönüşebilme özelliği nedeniyle selim bir lezyon kabul edilmesine rağmen, pre- malign bir lezyon olarak değerlendirilmesi önerilir. Olgumuzda da biopsi ile OFDBA tanısı sonrasında lokal rezeksiyon ve masif allogreft ile rekonstrüksiyon uygulanmıştır

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Cite This Article

Buldu, H., Centel, T., Kirimlioglu, H., Dirik, Y. (2015). Osteofibrous dysplasia-like adamantinoma in a 3-month-old male infant: a case report. Acta Orthopaedica et Traumatologica Turcica, Cilt: 49 Sayı: 2, 210–212. https://doi.org/10.3944/AOTT.2015.2809

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